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Cabrera-Beyrouti, E. Campos-Mollo, E. Rico-Santos, D.N. Jiménez-Rodríguez, M. Lledó-Riquelme, J. Vierna-García" "autores" => array:6 [ 0 => array:4 [ "nombre" => "R." "apellidos" => "Cabrera-Beyrouti" "email" => array:1 [ 0 => "rubeyrouthy@hotmail.com" ] "referencia" => array:2 [ 0 => array:2 [ "etiqueta" => "<span class="elsevierStyleSup">a</span>" "identificador" => "aff0005" ] 1 => array:2 [ "etiqueta" => "<span class="elsevierStyleSup">*</span>" "identificador" => "cor0005" ] ] ] 1 => array:3 [ "nombre" => "E." "apellidos" => "Campos-Mollo" "referencia" => array:1 [ 0 => array:2 [ "etiqueta" => "<span class="elsevierStyleSup">a</span>" "identificador" => "aff0005" ] ] ] 2 => array:3 [ "nombre" => "E." "apellidos" => "Rico-Santos" "referencia" => array:1 [ 0 => array:2 [ "etiqueta" => "<span class="elsevierStyleSup">a</span>" "identificador" => "aff0005" ] ] ] 3 => array:3 [ "nombre" => "D.N." "apellidos" => "Jiménez-Rodríguez" "referencia" => array:1 [ 0 => array:2 [ "etiqueta" => "<span class="elsevierStyleSup">a</span>" "identificador" => "aff0005" ] ] ] 4 => array:3 [ "nombre" => "M." "apellidos" => "Lledó-Riquelme" "referencia" => array:1 [ 0 => array:2 [ "etiqueta" => "<span class="elsevierStyleSup">a</span>" "identificador" => "aff0005" ] ] ] 5 => array:3 [ "nombre" => "J." "apellidos" => "Vierna-García" "referencia" => array:1 [ 0 => array:2 [ "etiqueta" => "<span class="elsevierStyleSup">b</span>" "identificador" => "aff0010" ] ] ] ] "afiliaciones" => array:2 [ 0 => array:3 [ "entidad" => "Departamento de Oftalmología, Hospital Virgen de los Lirios, Alcoy, Alicante, Spain" "etiqueta" => "a" "identificador" => "aff0005" ] 1 => array:3 [ "entidad" => "Departamento de Anatomía Patológica, Hospital Virgen de los Lirios, Alcoy, Alicante, Spain" "etiqueta" => "b" "identificador" => "aff0010" ] ] "correspondencia" => array:1 [ 0 => array:3 [ "identificador" => "cor0005" "etiqueta" => "⁎" "correspondencia" => "<span class="elsevierStyleItalic">Corresponding author</span>." ] ] ] ] "titulosAlternativos" => array:1 [ "es" => array:1 [ "titulo" => "Metástasis palpebral como primera manifestación de un tumor renal" ] ] "resumenGrafico" => array:2 [ "original" => 0 "multimedia" => array:7 [ "identificador" => "fig0015" "etiqueta" => "Fig. 3" "tipo" => "MULTIMEDIAFIGURA" "mostrarFloat" => true "mostrarDisplay" => false "figura" => array:1 [ 0 => array:4 [ "imagen" => "gr3.jpeg" "Alto" => 1792 "Ancho" => 1600 "Tamanyo" => 966139 ] ] "descripcion" => array:1 [ "en" => "<p id="spar0035" class="elsevierStyleSimplePara elsevierViewall">Immunohistochemical tests (400×) were positive for: (a) vimentin; (b) CD10; (c) EMA; (d) CAM 5.2; (e) AE1/AE3; (f) the tumor was negative for actine although the marker enabled the identification of blood vessels.</p>" ] ] ] "textoCompleto" => "<span class="elsevierStyleSections"><span id="sec0005" class="elsevierStyleSection elsevierViewall"><span class="elsevierStyleSectionTitle" id="sect0045">Introduction</span><p id="par0005" class="elsevierStylePara elsevierViewall">Malign eyelid lesions account for 24% of all palpebral lesions, including basal cell carcinoma (80%), squamous carcinoma (7%), malign melanoma (5%) and sebaceous gland carcinoma (3.2%).<a class="elsevierStyleCrossRef" href="#bib0050"><span class="elsevierStyleSup">1</span></a> However, eyelid metastasis is infrequent, accounting for under 1% of all eyelid malign lesions.<a class="elsevierStyleCrossRefs" href="#bib0055"><span class="elsevierStyleSup">2–4</span></a> Of all ocular metastases, the most commonly affected tissue is the uvea (63%), followed by the orbit (26%) and eyelids (10%).<a class="elsevierStyleCrossRef" href="#bib0070"><span class="elsevierStyleSup">5</span></a></p><p id="par0010" class="elsevierStylePara elsevierViewall">Generally, eyelid metastases occur in the context of a known primary cancer although on rare occasions an eyelid tumor is the first expression of a hidden carcinoma.<a class="elsevierStyleCrossRefs" href="#bib0065"><span class="elsevierStyleSup">4,6</span></a> The review of scientific literature<a class="elsevierStyleCrossRefs" href="#bib0060"><span class="elsevierStyleSup">3,4,6</span></a> carried out by the authors produced 66 eyelids metastatic disease cases. The most frequent primary tumors that cause metastases are breast carcinoma (20 eyes [30%]), followed by skin melanoma (13 [19.6%]) and uveal melanoma (7 [10.6%]). Only 5 eyes (7.5%) exhibited genitourinary origin.</p></span><span id="sec0010" class="elsevierStyleSection elsevierViewall"><span class="elsevierStyleSectionTitle" id="sect0050">Clinical case</span><p id="par0015" class="elsevierStylePara elsevierViewall">Male, 87, smoker, who developed a slow-growing nodule in the upper eyelid of the right eye. Examination revealed a nodule with slight eyelid edema without skin ulcerations or pain upon pressure. Corrected visual acuity (right eye: 0.2; left eye: 0.4) was explained by the presence of cataracts in both eyes. Remaining examination results such as extrinsic and intrinsic ocular motility, exophthalmometry, intraocular pressure and ophthalmoscopy were within normal ranges. Excisional biopsy was performed and during the procedure a 1<span class="elsevierStyleHsp" style=""></span>cm diameter well-defined tumor could be seen, with pigments and adherence to deep levels (<a class="elsevierStyleCrossRef" href="#fig0005">Fig. 1</a>). Histopathological examination revealed a round or elongated cell grouping made up of neoplastic cells with abundant transparent cytoplasm, defined by a network of fine vessels (<a class="elsevierStyleCrossRef" href="#fig0010">Fig. 2</a>a). Said cells exhibited a scarcity of cellular and nuclear pleomorphism. The PAS Schiff technique expressed abundant cytoplasm glycogen (<a class="elsevierStyleCrossRef" href="#fig0010">Fig. 2</a>b) and the immunohistochemical characteristics of the tumor were compatible with renal cell carcinoma (RCC), positive for vimentin and CD10 (<a class="elsevierStyleCrossRef" href="#fig0015">Fig. 3</a>).</p><elsevierMultimedia ident="fig0005"></elsevierMultimedia><elsevierMultimedia ident="fig0010"></elsevierMultimedia><elsevierMultimedia ident="fig0015"></elsevierMultimedia><p id="par0020" class="elsevierStylePara elsevierViewall">Extension study was initiated with computerized tomography which revealed a solid multi-lobulated renal tumor in each kidney measuring 7<span class="elsevierStyleHsp" style=""></span>cm in the right kidney and 9<span class="elsevierStyleHsp" style=""></span>cm in the left one, associated to left renal vein thrombosis. An additional solid 8<span class="elsevierStyleHsp" style=""></span>cm mass was identified in the right lumbar region and multiple pulmonary metastatic 2.5<span class="elsevierStyleHsp" style=""></span>cm nodules in the thorax (<a class="elsevierStyleCrossRef" href="#fig0020">Fig. 4</a>). At the orbit level, signal intensity of muscle structures and ocular globe was normal. Considering the context of RCC with multiple metastases in an elderly patient, it was decided to apply palliative treatment.</p><elsevierMultimedia ident="fig0020"></elsevierMultimedia></span><span id="sec0015" class="elsevierStyleSection elsevierViewall"><span class="elsevierStyleSectionTitle" id="sect0055">Discussion</span><p id="par0025" class="elsevierStylePara elsevierViewall">RCC is a malign neoplasia of tubular or ductal renal epithelial cells which accounts for 2–3% of malign tumors and 70–80% of all malign neoplasia that originate in the kidneys. The male-female ratio is of 3/2 and its highest incidence occurs between 50 and 70 years of age. Due to the retroperitoneal location of the kidney, many renal masses remain asymptomatic and are not palpable until the tumor is locally advanced.<a class="elsevierStyleCrossRef" href="#bib0080"><span class="elsevierStyleSup">7</span></a></p><p id="par0030" class="elsevierStylePara elsevierViewall">RCC metastases are present in 40% of patients at diagnostic.<a class="elsevierStyleCrossRef" href="#bib0085"><span class="elsevierStyleSup">8</span></a> The primary tumor could metastasize in any organ with lungs, liver, subcutaneous and bone tissue being the most common sites. However, ocular RCC metastases are infrequent and could precede diagnostic as in the present case or express years after nephrectomy.<a class="elsevierStyleCrossRefs" href="#bib0085"><span class="elsevierStyleSup">8,9</span></a> Ocular metastases usually involve the choroids, the iris and the ciliary body, with eyelid compromise being unusual.<a class="elsevierStyleCrossRef" href="#bib0090"><span class="elsevierStyleSup">9</span></a></p><p id="par0035" class="elsevierStylePara elsevierViewall">Kidney cell metastatic carcinoma is a diagnostic challenge. In general, patients with ocular metastases require a complete systemic assessment, ophthalmological examination and orbit imaging tests.<a class="elsevierStyleCrossRef" href="#bib0065"><span class="elsevierStyleSup">4</span></a></p><p id="par0040" class="elsevierStylePara elsevierViewall">The initial findings of eyelid metastases are nonspecific but can be classified in 4 types of lesions, i.e., painless subcutaneous nodules (62%), painless diffuse lesion (30%), solitary ulcerated lesion (8%) and nodules with acute inflammation simulating chalazion (5%).<a class="elsevierStyleCrossRef" href="#bib0055"><span class="elsevierStyleSup">2</span></a> The non-specificity of said signs and symptoms could mask metastatic lesions simulating different entities (chalazion, infections, benign tumors, xanthoma, squamous carcinoma, basal cell carcinoma, etc.). Therefore, metastatic disease must be considered in the differential diagnostic of eyelid lesions. Biopsy in suspect and/or recurrence lesions are particularly relevant.<a class="elsevierStyleCrossRef" href="#bib0060"><span class="elsevierStyleSup">3</span></a></p><p id="par0045" class="elsevierStylePara elsevierViewall">Immunohistochemistry is also an essential technique to assist in the identification of possible primary locations of eyelid metastases when the primary site is unknown.<a class="elsevierStyleCrossRefs" href="#bib0060"><span class="elsevierStyleSup">3,4</span></a></p><p id="par0050" class="elsevierStylePara elsevierViewall">In summary, eyelid metastases usually express in later stages of the disease as an expression of generalized metastatic carcinomatosis and occasionally could be the first expression when the site of the tumor is not known.<a class="elsevierStyleCrossRef" href="#bib0075"><span class="elsevierStyleSup">6</span></a> In these cases, ophthalmological examination could play an important role to diminish diagnostic delays and speed up treatment of the primary tumor.</p></span><span id="sec0020" class="elsevierStyleSection elsevierViewall"><span class="elsevierStyleSectionTitle" id="sect0060">Conflict of interests</span><p id="par0055" class="elsevierStylePara elsevierViewall">No conflict of interests was declared by the authors.</p></span></span>" "textoCompletoSecciones" => array:1 [ "secciones" => array:9 [ 0 => array:3 [ "identificador" => "xres933127" "titulo" => "Abstract" "secciones" => array:2 [ 0 => array:2 [ "identificador" => "abst0005" "titulo" => "Case report" ] 1 => array:2 [ "identificador" => "abst0010" "titulo" => "Discussion" ] ] ] 1 => array:2 [ "identificador" => "xpalclavsec907506" "titulo" => "Keywords" ] 2 => array:3 [ "identificador" => "xres933126" "titulo" => "Resumen" "secciones" => array:2 [ 0 => array:2 [ "identificador" => "abst0015" "titulo" => "Caso clínico" ] 1 => array:2 [ "identificador" => "abst0020" "titulo" => "Conclusión" ] ] ] 3 => array:2 [ "identificador" => "xpalclavsec907505" "titulo" => "Palabras clave" ] 4 => array:2 [ "identificador" => "sec0005" "titulo" => "Introduction" ] 5 => array:2 [ "identificador" => "sec0010" "titulo" => "Clinical case" ] 6 => array:2 [ "identificador" => "sec0015" "titulo" => "Discussion" ] 7 => array:2 [ "identificador" => "sec0020" "titulo" => "Conflict of interests" ] 8 => array:1 [ "titulo" => "References" ] ] ] "pdfFichero" => "main.pdf" "tienePdf" => true "fechaRecibido" => "2016-07-25" "fechaAceptado" => "2016-11-09" "PalabrasClave" => array:2 [ "en" => array:1 [ 0 => array:4 [ "clase" => "keyword" "titulo" => "Keywords" "identificador" => "xpalclavsec907506" "palabras" => array:6 [ 0 => "Eyelid" 1 => "Metastasis" 2 => "Ocular malignancy" 3 => "Ocular metastasis" 4 => "Renal cell carcinoma" 5 => "Renal tumor" ] ] ] "es" => array:1 [ 0 => array:4 [ "clase" => "keyword" "titulo" => "Palabras clave" "identificador" => "xpalclavsec907505" "palabras" => array:6 [ 0 => "Párpado" 1 => "Metástasis" 2 => "Malignidad ocular" 3 => "Metástasis ocular" 4 => "Carcinoma de células renales" 5 => "Tumor renal" ] ] ] ] "tieneResumen" => true "resumen" => array:2 [ "en" => array:3 [ "titulo" => "Abstract" "resumen" => "<span id="abst0005" class="elsevierStyleSection elsevierViewall"><span class="elsevierStyleSectionTitle" id="sect0010">Case report</span><p id="spar0005" class="elsevierStyleSimplePara elsevierViewall">An 87-year-old male presented with a slow-growing, painless and well defined nodule in the upper eyelid. The tumor measured 1<span class="elsevierStyleHsp" style=""></span>cm, and was pigmented and adhered to deep planes. The histopathology analysis was compatible with renal cell carcinoma. The extension study showed a tumor mass in each kidney, as well as multiple pulmonary metastases.</p></span> <span id="abst0010" class="elsevierStyleSection elsevierViewall"><span class="elsevierStyleSectionTitle" id="sect0015">Discussion</span><p id="spar0010" class="elsevierStyleSimplePara elsevierViewall">The ophthalmologist can play an important role in the diagnosis of metastatic cancer when eye disease is present. Therefore, the importance of a biopsy should be noted in those suspicious and/or recurrent lesions of the eyelid.</p></span>" "secciones" => array:2 [ 0 => array:2 [ "identificador" => "abst0005" "titulo" => "Case report" ] 1 => array:2 [ "identificador" => "abst0010" "titulo" => "Discussion" ] ] ] "es" => array:3 [ "titulo" => "Resumen" "resumen" => "<span id="abst0015" class="elsevierStyleSection elsevierViewall"><span class="elsevierStyleSectionTitle" id="sect0025">Caso clínico</span><p id="spar0015" class="elsevierStyleSimplePara elsevierViewall">Un varón de 87 años desarrolló en el párpado superior un nódulo de crecimiento lento, no doloroso y bien definido. El tumor de 1<span class="elsevierStyleHsp" style=""></span>cm de diámetro estaba pigmentado y adherido a planos profundos. El estudio anatomopatológico fue compatible con un carcinoma de células renales. El estudio de extensión mostró una masa tumoral en cada riñón y múltiples metástasis pulmonares.</p></span> <span id="abst0020" class="elsevierStyleSection elsevierViewall"><span class="elsevierStyleSectionTitle" id="sect0030">Conclusión</span><p id="spar0020" class="elsevierStyleSimplePara elsevierViewall">El oftalmólogo puede jugar un papel importante en el diagnóstico del cáncer metastásico, cuando la enfermedad ocular está presente. Por tanto, cabe destacar la relevancia de realizar una biopsia en aquellas lesiones sospechosas y/o recurrentes del párpado.</p></span>" "secciones" => array:2 [ 0 => array:2 [ "identificador" => "abst0015" "titulo" => "Caso clínico" ] 1 => array:2 [ "identificador" => "abst0020" "titulo" => "Conclusión" ] ] ] ] "NotaPie" => array:2 [ 0 => array:2 [ "etiqueta" => "☆" "nota" => "<p class="elsevierStyleNotepara" id="npar0005">Please cite this article as: Cabrera-Beyrouti R, Campos-Mollo E, Rico-Santos E, Jiménez-Rodríguez DN, Lledó-Riquelme M, Vierna-García J. Metástasis palpebral como primera manifestación de un tumor renal. Arch Soc Esp Oftalmol. 2017;92:547–551.</p>" ] 1 => array:2 [ "etiqueta" => "☆☆" "nota" => "<p class="elsevierStyleNotepara" id="npar0010">This paper was partially presented at the 92nd National Ophthalmology Congress held in Málaga, Spain, on 21–24 September, 2016.</p>" ] ] "multimedia" => array:4 [ 0 => array:7 [ "identificador" => "fig0005" "etiqueta" => "Fig. 1" "tipo" => "MULTIMEDIAFIGURA" "mostrarFloat" => true "mostrarDisplay" => false "figura" => array:1 [ 0 => array:4 [ "imagen" => "gr1.jpeg" "Alto" => 1567 "Ancho" => 1500 "Tamanyo" => 416142 ] ] "descripcion" => array:1 [ "en" => "<p id="spar0025" class="elsevierStyleSimplePara elsevierViewall">(a) Eyelid tumor section with a size of 1.09<span class="elsevierStyleHsp" style=""></span>×<span class="elsevierStyleHsp" style=""></span>0.9<span class="elsevierStyleHsp" style=""></span>cm; (b) macroscopic histological image of the eyelid tumor with hematoxylin–eosine staining (H&E 10×).</p>" ] ] 1 => array:7 [ "identificador" => "fig0010" "etiqueta" => "Fig. 2" "tipo" => "MULTIMEDIAFIGURA" "mostrarFloat" => true "mostrarDisplay" => false "figura" => array:1 [ 0 => array:4 [ "imagen" => "gr2.jpeg" "Alto" => 1402 "Ancho" => 950 "Tamanyo" => 535815 ] ] "descripcion" => array:1 [ "en" => "<p id="spar0030" class="elsevierStyleSimplePara elsevierViewall">(a) Pathological anatomy revealed cell groupings with broad, clear and well defined cytoplasm separated by trabeculae with highly vascularized stroma (H&E 400×); (b) the presence of glycogen in the cytoplasm of tumor cells was revealed utilizing the PAS Schiff technique (PAS 400×).</p>" ] ] 2 => array:7 [ "identificador" => "fig0015" "etiqueta" => "Fig. 3" "tipo" => "MULTIMEDIAFIGURA" "mostrarFloat" => true "mostrarDisplay" => false "figura" => array:1 [ 0 => array:4 [ "imagen" => "gr3.jpeg" "Alto" => 1792 "Ancho" => 1600 "Tamanyo" => 966139 ] ] "descripcion" => array:1 [ "en" => "<p id="spar0035" class="elsevierStyleSimplePara elsevierViewall">Immunohistochemical tests (400×) were positive for: (a) vimentin; (b) CD10; (c) EMA; (d) CAM 5.2; (e) AE1/AE3; (f) the tumor was negative for actine although the marker enabled the identification of blood vessels.</p>" ] ] 3 => array:7 [ "identificador" => "fig0020" "etiqueta" => "Fig. 4" "tipo" => "MULTIMEDIAFIGURA" "mostrarFloat" => true "mostrarDisplay" => false "figura" => array:1 [ 0 => array:4 [ "imagen" => "gr4.jpeg" "Alto" => 2311 "Ancho" => 2667 "Tamanyo" => 545011 ] ] "descripcion" => array:1 [ "en" => "<p id="spar0040" class="elsevierStyleSimplePara elsevierViewall">(a, b) Computerized tomography revealed the presence of the primary tumor in each kidney; (c) distal metastases in the pleural cavity of the left lung; (d) metastatic tumor mass in the right lumbar region.</p>" ] ] ] "bibliografia" => array:2 [ "titulo" => "References" "seccion" => array:1 [ 0 => array:2 [ "identificador" => "bibs0005" "bibliografiaReferencia" => array:9 [ 0 => array:3 [ "identificador" => "bib0050" "etiqueta" => "1" "referencia" => array:1 [ 0 => array:2 [ "contribucion" => array:1 [ 0 => array:2 [ "titulo" => "Lesions of the eyelids: a clinicopathological study" "autores" => array:1 [ 0 => array:2 [ "etal" => false "autores" => array:2 [ 0 => "A.L. 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Short communication
Eyelid metastasis as first presentation of renal cell carcinoma
Metástasis palpebral como primera manifestación de un tumor renal