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"apellidos" => "Tobalina Larrea" ] ] ] ] ] "idiomaDefecto" => "en" "Traduccion" => array:1 [ "es" => array:9 [ "pii" => "S2253654X15000979" "doi" => "10.1016/j.remn.2015.07.010" "estado" => "S300" "subdocumento" => "" "abierto" => array:3 [ "ES" => false "ES2" => false "LATM" => false ] "gratuito" => false "lecturas" => array:1 [ "total" => 0 ] "idiomaDefecto" => "es" "EPUB" => "https://multimedia.elsevier.es/PublicationsMultimediaV1/item/epub/S2253654X15000979?idApp=UINPBA00004N" ] ] "EPUB" => "https://multimedia.elsevier.es/PublicationsMultimediaV1/item/epub/S2253808915001160?idApp=UINPBA00004N" "url" => "/22538089/0000003500000001/v2_201704190137/S2253808915001160/v2_201704190137/en/main.assets" ] "en" => array:16 [ "idiomaDefecto" => true "cabecera" => "<span class="elsevierStyleTextfn">Interesting image</span>" "titulo" => "<span class="elsevierStyleSup">99m</span>Tc-MDP bone scintigraphies of three brothers affected by multiple osteochondromas" "tieneTextoCompleto" => true "paginas" => array:1 [ 0 => array:2 [ "paginaInicial" => "61" "paginaFinal" => "63" ] ] "autores" => array:1 [ 0 => array:4 [ "autoresLista" => "M.L. Dominguez, J.I. Rayo, J. Serrano, J.R. Infante, L. García, M. Moreno" "autores" => array:6 [ 0 => array:4 [ "nombre" => "M.L." "apellidos" => "Dominguez" "email" => array:1 [ 0 => "mluzovi@yahoo.es" ] "referencia" => array:1 [ 0 => array:2 [ "etiqueta" => "<span class="elsevierStyleSup">*</span>" "identificador" => "cor0005" ] ] ] 1 => array:2 [ "nombre" => "J.I." "apellidos" => "Rayo" ] 2 => array:2 [ "nombre" => "J." "apellidos" => "Serrano" ] 3 => array:2 [ "nombre" => "J.R." "apellidos" => "Infante" ] 4 => array:2 [ "nombre" => "L." "apellidos" => "García" ] 5 => array:2 [ "nombre" => "M." "apellidos" => "Moreno" ] ] "afiliaciones" => array:1 [ 0 => array:2 [ "entidad" => "Servicio de Medicina Nuclear, Hospital Universitario “Infanta Cristina”, Badajoz, Spain" "identificador" => "aff0005" ] ] "correspondencia" => array:1 [ 0 => array:3 [ "identificador" => "cor0005" "etiqueta" => "⁎" "correspondencia" => "Corresponding author." ] ] ] ] "titulosAlternativos" => array:1 [ "es" => array:1 [ "titulo" => "Gammagrafías óseas de cuerpo completo con <span class="elsevierStyleSup">99m</span>Tc-MDP de tres hermanos afectos de osteocondromatosis múltiple familiar" ] ] "resumenGrafico" => array:2 [ "original" => 0 "multimedia" => array:7 [ "identificador" => "fig0005" "etiqueta" => "Fig. 1" "tipo" => "MULTIMEDIAFIGURA" "mostrarFloat" => true "mostrarDisplay" => false "figura" => array:1 [ 0 => array:4 [ "imagen" => "gr1.jpeg" "Alto" => 950 "Ancho" => 1436 "Tamanyo" => 130545 ] ] "descripcion" => array:1 [ "en" => "<p id="spar0005" class="elsevierStyleSimplePara elsevierViewall">Anterior (A) and posterior (B) projections of <span class="elsevierStyleSup">99m</span>Tc-MDP bone scan showing pathological uptakes (arrows) corresponding to osteochondromas. At anterior (A) and posterior (B) projections of second bone scan it is shown slightly decreased uptake in osteochondroma at left humerus (green arrow) (shown at anteroposterior radiograph [E]) and increased tracer uptake in the one located at the inner side of the distal right femur (red arrow) (shown at anteroposterior radiograph [F]).</p>" ] ] ] "textoCompleto" => "<span class="elsevierStyleSections"><p id="par0005" class="elsevierStylePara elsevierViewall">Multiple osteochondromas (MO) is an autosomal dominant disorder and its prevalence is estimated at 1:50,000. Most patients are diagnosed by age 5–12 years, and it is based on the combination of two or more radiologically documented osteochondromas, with or without a positive family history.<a class="elsevierStyleCrossRef" href="#bib0020"><span class="elsevierStyleSup">1</span></a> The most common sites of involvement are distal femur, upper humerus and ankle. Usually it remains asymptomatic, and it is diagnosed in a family after the appearance of an index case,<a class="elsevierStyleCrossRef" href="#bib0025"><span class="elsevierStyleSup">2</span></a> although complications include cosmetic and osseous deformity, or neurovascular compromise. Malignant transformation is seen in 5% of patients, its average age is 30 years, and it is rare after 50 or before 10 years of age, so regular follow-up before skeletal maturation is not necessary unless the patient presents with clinical complaints.</p><p id="par0010" class="elsevierStylePara elsevierViewall">Although there is no specific consensus about the most proper method for the follow-up of patients with MO, they require continued surveillance to evaluate development of complications, specially malignant transformation.<a class="elsevierStyleCrossRef" href="#bib0030"><span class="elsevierStyleSup">3</span></a> These patients could routinely be seen each year or every two years, or if changes in their clinical condition occur. Hameetman et al.<a class="elsevierStyleCrossRef" href="#bib0020"><span class="elsevierStyleSup">1</span></a> recommend both plain radiographs of the scapulae and pelvis (areas that are not accessible to palpation, and asymptomatic malignant transformation can occur), in combination with follow-up <span class="elsevierStyleSup">99m</span>Tc bone scans. These scintigraphic studies can help in the identification of metabolically active osteochondromas by demonstrating increased radionuclide uptake, but after maduration they become no more active than normal bone. Nevertheless, in younger patients, this increased activity often persists well beyond the time of skeletal maturity because it is directly correlated with the degree of enchondral bone formation.<a class="elsevierStyleCrossRef" href="#bib0030"><span class="elsevierStyleSup">3</span></a> No new osteochondromas develop after skeletal maturation, so new increased uptake on bone scans should be regarded with suspicion. Although they can also be a result of trauma, bone infarct, inflammatory reaction…, sarcomatous degeneration must be discarded using dedicated MR imaging.</p><p id="par0015" class="elsevierStylePara elsevierViewall">We present the cases of three brothers previously diagnosed of MO by radiographs. There was no evidence of family history because social issues occurred:</p><p id="par0020" class="elsevierStylePara elsevierViewall"><span class="elsevierStyleItalic">Case 1</span>: A 18-year-old female underwent a whole-body bone scintigraphy (<a class="elsevierStyleCrossRef" href="#fig0005">Fig. 1</a>A and B) because of right knee pain. Four years later, this pain was increasing so another bone scan was performed (<a class="elsevierStyleCrossRef" href="#fig0005">Fig. 1</a>C and D) and it demonstrated increased uptake in that knee. MR discarded malignant transformation.</p><elsevierMultimedia ident="fig0005"></elsevierMultimedia><p id="par0025" class="elsevierStylePara elsevierViewall"><span class="elsevierStyleItalic">Case 2</span>: A 19-year-old male referred recurrent right patellar dislocation. Initial dynamic flow study and blood flow images of knees reflected normal vascular supply (images not shown). At bone scan, a focal intense uptake located at right knee (<a class="elsevierStyleCrossRef" href="#fig0010">Fig. 2</a>) forced to perform a MR, but it discarded osteosarcoma.</p><elsevierMultimedia ident="fig0010"></elsevierMultimedia><p id="par0030" class="elsevierStylePara elsevierViewall"><span class="elsevierStyleItalic">Case 3</span>: A 21-year-old male complaining left hip pain who underwent bone scan (<a class="elsevierStyleCrossRef" href="#fig0015">Fig. 3</a>). Multiple osteochondromas were seen, specially at left femur where a big one was located and it was responsible for the symptomatology.</p><elsevierMultimedia ident="fig0015"></elsevierMultimedia><p id="par0035" class="elsevierStylePara elsevierViewall">The increasing pain in lesions that were initially studied in each patient compelled to their resection 1.5–2 years later. Neither of three patients had suffered malignant transformation of any osteochondroma 3 years after scintigraphies were performed.</p><p id="par0040" class="elsevierStylePara elsevierViewall">With these images we confirm the advantage of obtaining whole-body images in a single examination, allowing assessing number, morphology and location of ostechondromas, and we observe the typical varied presentation, clinical symptoms and progress of MO, even within families.<a class="elsevierStyleCrossRef" href="#bib0030"><span class="elsevierStyleSup">3</span></a></p></span>" "pdfFichero" => "main.pdf" "tienePdf" => true "fechaRecibido" => "2015-05-22" "fechaAceptado" => "2015-07-06" "NotaPie" => array:1 [ 0 => array:2 [ "etiqueta" => "☆" "nota" => "<p class="elsevierStyleNotepara" id="npar0005">Please cite this article as: Dominguez ML, Rayo JI, Serrano J, Infante JR, García L, Moreno M. Gammagrafías óseas de cuerpo completo con <span class="elsevierStyleSup">99m</span>Tc-MDP de tres hermanos afectos de osteocondromatosis múltiple familiar. Rev Esp Med Nucl Imagen Mol. 2016;35:61–63.</p>" ] ] "multimedia" => array:3 [ 0 => array:7 [ "identificador" => "fig0005" "etiqueta" => "Fig. 1" "tipo" => "MULTIMEDIAFIGURA" "mostrarFloat" => true "mostrarDisplay" => false "figura" => array:1 [ 0 => array:4 [ "imagen" => "gr1.jpeg" "Alto" => 950 "Ancho" => 1436 "Tamanyo" => 130545 ] ] "descripcion" => array:1 [ "en" => "<p id="spar0005" class="elsevierStyleSimplePara elsevierViewall">Anterior (A) and posterior (B) projections of <span class="elsevierStyleSup">99m</span>Tc-MDP bone scan showing pathological uptakes (arrows) corresponding to osteochondromas. At anterior (A) and posterior (B) projections of second bone scan it is shown slightly decreased uptake in osteochondroma at left humerus (green arrow) (shown at anteroposterior radiograph [E]) and increased tracer uptake in the one located at the inner side of the distal right femur (red arrow) (shown at anteroposterior radiograph [F]).</p>" ] ] 1 => array:7 [ "identificador" => "fig0010" "etiqueta" => "Fig. 2" "tipo" => "MULTIMEDIAFIGURA" "mostrarFloat" => true "mostrarDisplay" => false "figura" => array:1 [ 0 => array:4 [ "imagen" => "gr2.jpeg" "Alto" => 1889 "Ancho" => 1800 "Tamanyo" => 205959 ] ] "descripcion" => array:1 [ "en" => "<p id="spar0010" class="elsevierStyleSimplePara elsevierViewall">Pathological uptakes (arrows) seen at anterior (A) and posterior (B) projections of <span class="elsevierStyleSup">99m</span>Tc-MDP whole-body study corresponding to osteochondromas. At axial MR images (C), we show the one located at the outer side of the right distal femur.</p>" ] ] 2 => array:7 [ "identificador" => "fig0015" "etiqueta" => "Fig. 3" "tipo" => "MULTIMEDIAFIGURA" "mostrarFloat" => true "mostrarDisplay" => false "figura" => array:1 [ 0 => array:4 [ "imagen" => "gr3.jpeg" "Alto" => 1953 "Ancho" => 1800 "Tamanyo" => 224243 ] ] "descripcion" => array:1 [ "en" => "<p id="spar0015" class="elsevierStyleSimplePara elsevierViewall">Anterior (A) and posterior (B) projections of <span class="elsevierStyleSup">99m</span>Tc-MDP bone scan showing multiple pathological uptakes (arrows) corresponding to osteochondromas. Moderate FDG uptake is seen at the big one located at the left proximal femur (red arrow), that it is also shown at coronal MR slice (C).</p>" ] ] ] "bibliografia" => array:2 [ "titulo" => "References" "seccion" => array:1 [ 0 => array:2 [ "identificador" => "bibs0005" "bibliografiaReferencia" => array:3 [ 0 => array:3 [ "identificador" => "bib0020" "etiqueta" => "1" "referencia" => array:1 [ 0 => array:2 [ "contribucion" => array:1 [ 0 => array:2 [ "titulo" => "Multiple osteochondromas: clinicopathological and genetic spectrum and suggestions for clinical management" "autores" => array:1 [ 0 => array:2 [ "etal" => false "autores" => array:5 [ 0 => "L. Hameetman" 1 => "J.V.M.G. Bovee" 2 => "A.H.M. Taminiau" 3 => "M.H. Kroon" 4 => "P.C.W. 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Interesting image
99mTc-MDP bone scintigraphies of three brothers affected by multiple osteochondromas
Gammagrafías óseas de cuerpo completo con 99mTc-MDP de tres hermanos afectos de osteocondromatosis múltiple familiar
M.L. Dominguez
, J.I. Rayo, J. Serrano, J.R. Infante, L. García, M. Moreno
Autor para correspondencia
Servicio de Medicina Nuclear, Hospital Universitario “Infanta Cristina”, Badajoz, Spain