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The presence of gas can also be seen in the adjacent soft tissues (A and C).</p>" ] ] ] "textoCompleto" => "<span class="elsevierStyleSections"><p id="par0005" class="elsevierStylePara elsevierViewall">Emphysematous osteomyelitis (EO) is an extremely rare infection caused by gas-producing bacteria.<a class="elsevierStyleCrossRef" href="#bib0005"><span class="elsevierStyleSup">1</span></a> It has high morbidity and mortality rates, which means it requires an early and aggressive therapeutic approach.<a class="elsevierStyleCrossRef" href="#bib0010"><span class="elsevierStyleSup">2</span></a> We present a case of EO of the hip with poor progress in a patient who presented with septic shock. We show a characteristic radiological sign which was key to establishing the suspected diagnosis.</p><p id="par0010" class="elsevierStylePara elsevierViewall">This was a 52-year-old woman with a history of type II Chiari malformation with secondary paraplegia who was brought to Accident and Emergency due to disorientation and low level of consciousness for a number of hours.</p><p id="par0015" class="elsevierStylePara elsevierViewall">On arrival at the hospital she was stuporous, tachypnoeic and tachycardic. Examination revealed the presence of a pressure ulcer in the right gluteus developed in the previous month and managed at home with topical wound care, despite which it had increased in extension and depth.</p><p id="par0020" class="elsevierStylePara elsevierViewall">The analysis revealed leucocytosis (19,200 leucocytes/μl) and elevated C-reactive protein (CRP) (>25<span class="elsevierStyleHsp" style=""></span>mg/dl). Brain computed tomography (CT) and chest x-ray showed no abnormalities.</p><p id="par0025" class="elsevierStylePara elsevierViewall">The patient's level of consciousness deteriorated and she became haemodynamically unstable, requiring admission to the ICU.</p><p id="par0030" class="elsevierStylePara elsevierViewall">Given the suspicion of sepsis with a focus on the skin and soft tissues, an CT of abdomen and pelvis with contrast was requested (<a class="elsevierStyleCrossRef" href="#fig0005">Fig. 1</a>), which showed findings compatible with EO.</p><elsevierMultimedia ident="fig0005"></elsevierMultimedia><p id="par0035" class="elsevierStylePara elsevierViewall">The Orthopaedics and Trauma Department was contacted, and they performed urgent surgery with resection of the right femoral head, cleaning and debridement.</p><p id="par0040" class="elsevierStylePara elsevierViewall">Initially, she was given empirical antibiotic therapy with meropenem, linezolid and amikacin. The following were isolated in blood cultures without antibiotic pressure: <span class="elsevierStyleItalic">Streptococcus anginosus, Streptococcus constellatus, Bacteroides fragilis</span> group, <span class="elsevierStyleItalic">Clostridium ramosum</span> (2/2). Cultures of bone and periarticular tissue after surgery grew: <span class="elsevierStyleItalic">Escherichia coli, Streptococcus anginosus, Streptococcus constellatus, Eikenella corrodens, Clostridium</span> spp., <span class="elsevierStyleItalic">Prevotella intermedia, Parvimonas micra</span> and <span class="elsevierStyleItalic">Bacteroides caccae.</span></p><p id="par0045" class="elsevierStylePara elsevierViewall">After the above isolations, the antibiotic therapy was adjusted to piperacillin/tazobactam, ciprofloxacin and daptomycin. Given the probable involvement of anaerobic bacteria (<span class="elsevierStyleItalic">Clostridium</span> spp. and <span class="elsevierStyleItalic">Bacteroides</span> spp.), metronidazole was added to the combination after performing antibiotic sensitivity tests.</p><p id="par0050" class="elsevierStylePara elsevierViewall">The patient made very slow progress, with the need for drainage of collections and debridement of pressure ulcers. After more than four months in hospital, the focus was under control and the patient was discharged.</p><p id="par0055" class="elsevierStylePara elsevierViewall">The presence of intraosseous gas was described for the first time in 1981.<a class="elsevierStyleCrossRef" href="#bib0015"><span class="elsevierStyleSup">3</span></a> When it is identified in the vertebral bodies, it is usually related to non-infectious causes.<a class="elsevierStyleCrossRef" href="#bib0005"><span class="elsevierStyleSup">1</span></a> In contrast, in the extra-axial skeleton, it is a finding highly suggestive of EO.<a class="elsevierStyleCrossRef" href="#bib0020"><span class="elsevierStyleSup">4</span></a></p><p id="par0060" class="elsevierStylePara elsevierViewall">EO is a serious bone infection with very few cases described in the literature.<a class="elsevierStyleCrossRef" href="#bib0005"><span class="elsevierStyleSup">1</span></a> It is generally produced by haematogenous or contiguous spread. In the first case, monomicrobial infections predominate, while in the second, polymicrobial infections.<a class="elsevierStyleCrossRef" href="#bib0010"><span class="elsevierStyleSup">2</span></a> When it spreads by contiguity, it is usually derived from an intra-abdominal infection, spinal surgery, or skin and soft tissue infection (SSTI).<a class="elsevierStyleCrossRef" href="#bib0025"><span class="elsevierStyleSup">5</span></a></p><p id="par0065" class="elsevierStylePara elsevierViewall">The identification of polymicrobial bacteraemia should alert to the presence of an uncontrolled focus, generally intra-abdominal.<a class="elsevierStyleCrossRef" href="#bib0030"><span class="elsevierStyleSup">6</span></a> In our patient, we suspect that the most likely mechanism was the deep extension of an SSTI due to her history of pressure ulcer with adjacent pyomyositis and arthritis. This case illustrates the importance of adequate management of chronic wounds and pressure sores, as they can be a focus of polymicrobial bacteraemia.</p><p id="par0070" class="elsevierStylePara elsevierViewall">From the microbiology point of view, anaerobic bacteria and enterobacteria are usually isolated<a class="elsevierStyleCrossRef" href="#bib0035"><span class="elsevierStyleSup">7</span></a> In our case it was a polymicrobial infection with predominance of <span class="elsevierStyleItalic">Clostridium</span> spp. and <span class="elsevierStyleItalic">Bacteroides</span> spp. Given the severity of anaerobic bacteraemia, antibiotic sensitivity tests must be performed to confirm the sensitivity of these species to metronidazole, piperacillin/tazobactam and carbapenems, as sensitivity can vary between different species and strains.<a class="elsevierStyleCrossRef" href="#bib0040"><span class="elsevierStyleSup">8</span></a></p><p id="par0075" class="elsevierStylePara elsevierViewall">Contrast-enhanced CT is the most sensitive test for diagnosing EO, showing the “pumice stone sign” in more than 90% of cases. Other typical radiographic findings are emphysema in the surrounding soft tissues and the absence of destruction of the cortical bone.<a class="elsevierStyleCrossRef" href="#bib0005"><span class="elsevierStyleSup">1</span></a></p><p id="par0080" class="elsevierStylePara elsevierViewall">Treatment is combined with parenteral broad-spectrum antibiotic therapy for at least four weeks and surgical control of the focus.<a class="elsevierStyleCrossRefs" href="#bib0005"><span class="elsevierStyleSup">1,4,9</span></a></p><p id="par0085" class="elsevierStylePara elsevierViewall">It is important to define the optimal duration of antibiotic therapy and the need for surgical intervention in all cases, as multiple or complex surgical interventions can increase mortality rates.<a class="elsevierStyleCrossRef" href="#bib0045"><span class="elsevierStyleSup">9</span></a></p><span id="sec0005" class="elsevierStyleSection elsevierViewall"><span class="elsevierStyleSectionTitle" id="sect0005">Funding</span><p id="par0090" class="elsevierStylePara elsevierViewall">The authors declare that they did not receive any funding.</p></span><span id="sec0010" class="elsevierStyleSection elsevierViewall"><span class="elsevierStyleSectionTitle" id="sect0010">Authorship</span><p id="par0095" class="elsevierStylePara elsevierViewall">All authors contributed to the preparation of the article.</p></span><span id="sec0015" class="elsevierStyleSection elsevierViewall"><span class="elsevierStyleSectionTitle" id="sect0015">Conflicts of interest</span><p id="par0100" class="elsevierStylePara elsevierViewall">There are no conflicts of interest in the preparation of this article.</p></span></span>" "textoCompletoSecciones" => array:1 [ "secciones" => array:4 [ 0 => array:2 [ "identificador" => "sec0005" "titulo" => "Funding" ] 1 => array:2 [ "identificador" => "sec0010" "titulo" => "Authorship" ] 2 => array:2 [ "identificador" => "sec0015" "titulo" => "Conflicts of interest" ] 3 => array:1 [ "titulo" => "References" ] ] ] "pdfFichero" => "main.pdf" "tienePdf" => true "multimedia" => array:1 [ 0 => array:8 [ "identificador" => "fig0005" "etiqueta" => "Figure 1" "tipo" => "MULTIMEDIAFIGURA" "mostrarFloat" => true "mostrarDisplay" => false "figura" => array:1 [ 0 => array:4 [ "imagen" => "gr1.jpeg" "Alto" => 705 "Ancho" => 2217 "Tamanyo" => 172503 ] ] "detalles" => array:1 [ 0 => array:3 [ "identificador" => "at0035" "detalle" => "Figure " "rol" => "short" ] ] "descripcion" => array:1 [ "en" => "<p id="spar0005" class="elsevierStyleSimplePara elsevierViewall">Extensive inflammatory process mainly involving the components of the right hip, with the presence of gas in the thickness of the bone of the femoral head ("pumice stone sign") (A and C), in the iliac acetabulum and in the right femoroacetabular joint (B). The presence of gas can also be seen in the adjacent soft tissues (A and C).</p>" ] ] ] "bibliografia" => array:2 [ "titulo" => "References" "seccion" => array:1 [ 0 => array:2 [ "identificador" => "bibs0005" "bibliografiaReferencia" => array:9 [ 0 => array:3 [ "identificador" => "bib0005" "etiqueta" => "1" "referencia" => array:1 [ 0 => array:2 [ "contribucion" => array:1 [ 0 => array:2 [ "titulo" => "Diagnostic features of emphysematous osteomyelitis" "autores" => array:1 [ 0 => array:2 [ "etal" => false "autores" => array:4 [ 0 => "J.E. Small" 1 => "P. Chea" 2 => "N. Shah" 3 => "K.M. Small" ] ] ] ] ] "host" => array:1 [ 0 => array:2 [ "doi" => "10.1067/j.cpradiol.2018.05.008" "Revista" => array:6 [ "tituloSerie" => "Curr Probl Diagn Radiol." 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Scientific letter
Available online 2 August 2024
Emphysematous osteomyelitis of the hip and iliac bone: Serious infection with a characteristic radiographic finding
Osteomielitis enfisematosa de cadera y hueso ilíaco: infección grave con una imagen radiográfica característica