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El examen físico reveló dolor abdominal en cuadrante superior derecho e ictericia. Laboratorios con leucocitosis (12.000<span class="elsevierStyleHsp" style=""></span>ml), elevación de ALT 63<span class="elsevierStyleHsp" style=""></span>U/l, AST 175<span class="elsevierStyleHsp" style=""></span>U/l, bilirrubina total de 6,7<span class="elsevierStyleHsp" style=""></span>mg/dl y fosfatasa alcalina de 163<span class="elsevierStyleHsp" style=""></span>U/l.</p><p id="par0010" class="elsevierStylePara elsevierViewall">Se realizó una tomografía abdominal por antecedente del paciente y se evidencia una fuga protésica grado II. La ecografía abdominal demostró paredes vesiculares engrosadas. La colangiorresonancia mostró imágenes sugestivas de cuerpos de Von Meyenburg y ausencia de obstrucción biliar (<a class="elsevierStyleCrossRefs" href="#fig0005">figs. 1 y 2</a>). El paciente evoluciona favorablemente y continuó con vigilancia clínica ambulatoria.</p><elsevierMultimedia ident="fig0005"></elsevierMultimedia><elsevierMultimedia ident="fig0010"></elsevierMultimedia><p id="par0015" class="elsevierStylePara elsevierViewall">Los hamartomas biliares múltiples (HBM) son malformaciones benignas raras de los conductos biliares intra-hepáticos; descrito por primera vez por Von Meyenburg en 1955<a class="elsevierStyleCrossRef" href="#bib0020"><span class="elsevierStyleSup">1</span></a>. Los HBM aparecen en el 0,9% de los niños y en el 5,6% de los adultos. Se puede visualizar un artefacto de «centelleo», debido a las reverberaciones que producen los cristales de colesterol que llenan los conductos dilatados. La resonancia magnética proporciona una mayor sensibilidad y especificidad<a class="elsevierStyleCrossRef" href="#bib0025"><span class="elsevierStyleSup">2</span></a>. El HBM es una enfermedad asintomática, benigna<a class="elsevierStyleCrossRef" href="#bib0030"><span class="elsevierStyleSup">3</span></a> y no requiere tratamiento específico.</p></span>" "pdfFichero" => "main.pdf" "tienePdf" => true "multimedia" => array:2 [ 0 => array:7 [ "identificador" => "fig0005" "etiqueta" => "Figura 1" "tipo" => "MULTIMEDIAFIGURA" "mostrarFloat" => true "mostrarDisplay" => false "figura" => array:1 [ 0 => array:4 [ "imagen" => "gr1.jpeg" "Alto" => 1449 "Ancho" => 1508 "Tamanyo" => 159940 ] ] "descripcion" => array:1 [ "es" => "<p id="spar0005" class="elsevierStyleSimplePara elsevierViewall">Los cuerpos de Von Meyenburg dan una apariencia de cielo estrellado.</p>" ] ] 1 => array:7 [ "identificador" => "fig0010" "etiqueta" => "Figura 2" "tipo" => "MULTIMEDIAFIGURA" "mostrarFloat" => true "mostrarDisplay" => false "figura" => array:1 [ 0 => array:4 [ "imagen" => "gr2.jpeg" "Alto" => 972 "Ancho" => 1508 "Tamanyo" => 60348 ] ] "descripcion" => array:1 [ "es" => "<p id="spar0010" class="elsevierStyleSimplePara elsevierViewall">Múltiples imágenes de apariencia microquística en el parénquima hepático.</p>" ] ] ] "bibliografia" => array:2 [ "titulo" => "Bibliografía" "seccion" => array:1 [ 0 => array:2 [ "identificador" => "bibs0015" "bibliografiaReferencia" => array:3 [ 0 => array:3 [ "identificador" => "bib0020" "etiqueta" => "1" "referencia" => array:1 [ 0 => array:2 [ "contribucion" => array:1 [ 0 => array:2 [ "titulo" => "Calcification in biliary hamartomatosis" "autores" => array:1 [ 0 => array:2 [ "etal" => false "autores" => array:4 [ 0 => "D. 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Un cielo estrellado por Von Meyenburg: hamartomatosis biliar
Jerónimo Toro-Calle, Alejandro Concha, Reinaldo Rincón, Cristian Pinzón
10.1016/j.gastrohep.2021.01.006Gastroenterol Hepatol. 2022;45:470-1
This article is available in English
A starry sky by Von Meyenburg: Biliary hamartomatosis
Jerónimo Toro-Calle, Alejandro Concha, Reinaldo Rincón, Cristian Pinzón
10.1016/j.gastre.2021.01.006Gastroenterol Hepatol. 2022;45:470-1